Host species-specific mutations in the thumb domain of the 3Dpol polymerase are required for efficient replication of human hepatitis A virus in mice.

Ichiro Misumi1 Takayoshi Shirasaki2 Ling Xie3 Bryan Yonish4 Olga González-López2 Asuka Hirai-Yuki2 Xian Chen3,4 You Li5 Jason K Whitmire1,2,4 Stanley M Lemon2,4,6
Affiliations 6 institutions
  1. Department of Genetics, The University of North Carolina at Chapel Hill, Chapel Hill, North Carolina, United States of America.
  2. Department of Microbiology & Immunology, The University of North Carolina at Chapel Hill, Chapel Hill, North Carolina, United States of America.
  3. Department of Biochemistry and Biophysics, The University of North Carolina at Chapel Hill, Chapel Hill, North Carolina, United States of America.
  4. Lineberger Comprehensive Cancer Center, The University of North Carolina at Chapel Hill, Chapel Hill, North Carolina, United States of America.
  5. Department of Pediatrics, The University of North Carolina at Chapel Hill, Chapel Hill, North Carolina, United States of America.
  6. Department of Medicine, The University of North Carolina at Chapel Hill, Chapel Hill, North Carolina, United States of America.

Abstract

Hepatitis A virus (HAV) is a globally important cause of enterically-transmitted hepatitis. It is one of 9 distinct Hepatovirus species in the Picornaviridae, among which phylogenetic reconstructions suggest multiple past host species jumps. HAV readily infects mice with defective type I interferon responses, suggesting the major barrier preventing human HAV from replicating in a rodent host is an inability to overcome innate immune responses. In prior studies, only a single nonsynonymous mutation of uncertain significance (3Dpol-R468K) was identified within the genome of wild-type HAV following passage in interferon-receptor knockout mice. Here, we show that R468K and other mutations in the 3Dpol polymerase (E461D and D473G) are uniformly present in virus recovered from Ifnar1-/- mice following intrahepatic injection of HAV RNA. Reverse molecular genetics experiments confirmed RNAs with R468K or D473G mutations were more likely to initiate sustained infection than wild-type RNA in mice. In competition experiments using cell culture-adapted virus, a K468 mutant out-replicated wild-type R468 in murine cells, whereas R468 rapidly replaced K468 in human cells. These 3Dpol mutations thus promote HAV replication in a host species-specific manner. AlphaFold 3 modeling indicates E461, R468, and D473 are closely positioned on the surface of the 3Dpol thumb domain, suggesting they modulate interactions with species-specific host factor(s). Proteomics analysis of proteins co-precipitating with HA-3Dpol expressed in Huh-7.5 cells identified heat shock 70 protein HSPA8 and its co-chaperone, BAG2. HSPA8 is known to be a critical hepatovirus host factor and HAV genome replication is highly dependent upon heat shock chaperone activity. The mouse-adaptive R468K mutation enhances co-immunoprecipitation of 3Dpol with murine HSPA8 and BAG2, suggesting it facilitates chaperone-dependent acquisition of polymerase function in mouse cells. Our results identify a non-immune barrier to HAV replication in mice and enable future reverse molecular genetics studies in a small animal model.

Supporting text Virus Host Location
Hepatitis A 1 Hepatitis A virus 2 Virus Replication 191 Animals 1948 Humans 1440 Mice 253 Mice, Knockout 7 Mutation 209 Species Specificity 84

Evidence records

1 total
Functional Mechanism
1 records · 1 evidence types
Evidence type
1 records
OVE11046
Key finding

Mutations R468K, E461D, and D473G in the 3Dpol polymerase of Hepatitis A virus enhance replication efficiency specifically in Ifnar1-/- mice, functioning as host species-specific adaptive changes.

Virus
Host
Not specified
Location
Not specified
Supporting text

Here, we show that R468K and other mutations in the 3Dpol polymerase (E461D and D473G) are uniformly present in virus recovered from Ifnar1-/- mice following intrahepatic injection of HAV RNA. Reverse molecular genetics experiments confirmed RNAs with R468K or D473G mutations were more likely to initiate sustained infection than wild-type RNA in mice.

Genes or proteins
3Dpol polymerase
Mutations
R468K | E461D | D473G
Mechanism types
replication adaptation | host-range expansion